Title
Mediator of DNA damage checkpoint protein 1 facilitates V(D)J recombination in cells lacking DNA repair factor XLF
Date Issued
01 January 2020
Access level
open access
Resource Type
journal article
Author(s)
Norwegian University of Science and Technology
Publisher(s)
MDPI AG
Abstract
DNA double-strand breaks (DSBs) trigger the Ataxia telangiectasia mutated (ATM)-dependent DNA damage response (DDR), which consists of histone H2AX, MDC1, RNF168, 53BP1, PTIP, RIF1, Rev7, and Shieldin. Early stages of B and T lymphocyte development are dependent on recombination activating gene (RAG)-induced DSBs that form the basis for further V(D)J recombination. Non-homologous end joining (NHEJ) pathway factors recognize, process, and ligate DSBs. Based on numerous loss-of-function studies, DDR factors were thought to be dispensable for the V(D)J recombination. In particular, mice lacking Mediator of DNA Damage Checkpoint Protein 1 (MDC1) possessed nearly wild-type levels of mature B and T lymphocytes in the spleen, thymus, and bone marrow. NHEJ factor XRCC4-like factor (XLF)/Cernunnos is functionally redundant with ATM, histone H2AX, and p53-binding protein 1 (53BP1) during the lymphocyte development in mice. Here, we genetically inactivated MDC1, XLF, or both MDC1 and XLF in murine vAbl pro-B cell lines and, using chromosomally integrated substrates, demonstrated that MDC1 stimulates the V(D)J recombination in cells lacking XLF. Moreover, combined inactivation of MDC1 and XLF in mice resulted in synthetic lethality. Together, these findings suggest that MDC1 and XLF are functionally redundant during the mouse development, in general, and the V(D)J recombination, in particular.
Volume
10
Issue
1
Language
English
OCDE Knowledge area
Genética, Herencia
Inmunología
Subjects
Scopus EID
2-s2.0-85077307911
PubMed ID
Source
Biomolecules
ISSN of the container
2218273X
Sponsor(s)
Funding: This work was supported by the Research Council of Norway Young Talent Investigator grant (#249774) to V.O. In addition, Oksenych group was supported by the Liaison Committee for education, research, and innovation in Central Norway (#13477; #38881), the Norwegian Cancer Society (#182355), FRIMEDBIO grants (#270491 and #291217), and The Outstanding Academic Fellow Program at NTNU (2017–2021).
Sources of information:
Directorio de Producción Científica
Scopus